Case Reports
16 April 2024
Vol. 46 No. 1 (2024)
https://doi.org/10.4081/pmc.2024.332

Dysphagia lusoria caused by aberrant right subclavian artery associated with truncus bicaroticus in an 8-month-old girl. Case report and review of literature

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Dysphagia lusoria, case report, aberrant right subclavian artery
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Authors

Melpomeni Bizhga
https://orcid.org/0000-0002-9942-2929
Service of Pediatric Pneumology, Mother Teresa Hospital, Tirana, Albania.
Virtut Velmishi
tutimodh@yahoo.com
https://orcid.org/0000-0003-1648-7258
Service of Pediatric Gastroenterology, Mother Teresa Hospital, Tirana, Albania.
Lorena Sila
https://orcid.org/0009-0003-9346-4639
Pediatric Department, Mother Teresa Hospital, Tirana, Albania.
Albert Koja
Service of Pediatric Cardiology, Mother Teresa Hospital, Tirana, Albania.
Stiljan Hoxha
https://orcid.org/0000-0003-1984-6172
Division of Cardiac Surgery, Department of Surgery, Dentistry, Pediatrics and Gynecology, University of Verona, Italy.

Dysphagia lusoria is a rare pediatric condition caused by extrinsic compression of the esophagus by an abnormal subclavian artery. The most common congenital abnormality in aortic arch development is an aberrant right subclavian artery. The retroesophageal right subclavian artery is typically symptomatic in 10-33% of cases. The patient, an 8-month-old girl with a history of early dysphagia and stridor, was diagnosed with an abnormal right subclavian artery. She was admitted to the pneumology service multiple times due to stridor, vomiting, and failure to thrive. During hospitalization at the gastroenterology service, a barium swallow and an upper digestive endoscopy indicated an abnormal right subclavian artery, which was confirmed by an Angiography CT scan. She underwent surgery at the age of sixteen months. All symptoms are resolved following surgical intervention, and the patient is still asymptomatic and in good clinical condition 12 months later. Every physician should be aware of abnormal right subclavian arteries and their clinical symptoms in children and adults in order to recognize and diagnose them early. Only an early evaluation may reduce complications such as delayed physical growth, dysphagia, and recurrent respiratory infections.

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Natsis K, Didagelos M, Gkiouliava A, et al. The aberrant right subclavian artery: cadaveric study and literature review. Surg Radiol Anat 2017;39:559–65. Erratum in: Surg Radiol Anat 2017 Sep 14.
Kieffer E, Bahnini A, Koskas F. Aberrant subclavian artery: surgical treatment in thirty-three adult patients. J Vasc Surg 1994;19:100e11. DOI: https://doi.org/10.1016/S0741-5214(94)70125-3
Molz G, Burri B. Aberrant subclavian artery (Arteria lusoria): sex differences in the prevalence of various forms of the malformation. Evaluation of 1378 observations. Virchows Archiv A: Pathological Anatomy and Histology 1978;380:303–15. DOI: https://doi.org/10.1007/BF00431315
Myers PO, Fasel JHD, Kalangos A, Gailtoud P. Arteria lusoria: Developmental anatomy, clinical, radiological and surgical aspects. Ann Cardiol Angeiol 2010;59:147–54. DOI: https://doi.org/10.1016/j.ancard.2009.07.008
Natsis K, Didagelos M, Gkiouliava A, et al. The aberrant right subclavian artery: cadaveric study and literal review. Surg Radiol Anat 2017;39:559–65. DOI: https://doi.org/10.1007/s00276-016-1796-5
Pantvaidya GH, Mistry RC, Ghanekar VR, et al. Injury of an aberrant subclavian artery: a rare complication of video assisted thoracoscopic esophagectomy. Ann Thorac Cardiovasc Surg 2005;11:35–7.
Janssen M, Baggen MGA, Veen HF, et al. Dysphagia lusoria: clinical aspects, manometric findings, diagnosis, and therapy. Am J Gastroenterol 2000;95:1411–6. DOI: https://doi.org/10.1111/j.1572-0241.2000.02071.x
Ulger Z, Ozyurek AR, Levent E, et al. Arteria lusoria as a cause of dysphagia. Acta Cardiologica 2004;59:445–7. DOI: https://doi.org/10.2143/AC.59.4.2005213
Karcaaltincaba M, Haliloglu M, Ozkan E, et al. Non-invasive imaging of aberrant right subclavian artery pathologies and aberrant right vertebral artery. Br J Radiol 2009;82:73–8. DOI: https://doi.org/10.1259/bjr/44929969
Moore KL, Persaud TVN. The developing human: clinically oriented embryology. 6th Ed. Philadelphia: WB Saunders Co.; 1998. pp. 384–394.
Nelson JS, Hurtado CG, Wearden PD. Surgery for Dysphagia Lusoria in Children. Ann Thoracic Surg 2020;109:e131–3. DOI: https://doi.org/10.1016/j.athoracsur.2019.05.058

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Dysphagia lusoria caused by aberrant right subclavian artery associated with truncus bicaroticus in an 8-month-old girl. Case report and review of literature. (2024). La Pediatria Medica E Chirurgica, 46(1). https://doi.org/10.4081/pmc.2024.332
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